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Anomalous origin of the left coronary artery from the right pulmonary artery in a univentricular heart

Published online by Cambridge University Press:  27 June 2017

Ziyad M. Binsalamah ,
Diego A. Lara  and
Emmett D. McKenzie
Ziyad M. Binsalamah*
Affiliation:
Michael E. DeBakey Department of Surgery, Division of Congenital Heart Surgery, Baylor College of Medicine, Houston, Texas, United States of America
Diego A. Lara
Affiliation:
Division of Pediatric Cardiology, Texas Children’s Hospital, Baylor College of Medicine, Houston, Texas, United States of America
Emmett D. McKenzie
Affiliation:
Michael E. DeBakey Department of Surgery, Division of Congenital Heart Surgery, Baylor College of Medicine, Houston, Texas, United States of America
*
Correspondence to: Z. M. Binsalamah, Michael E. DeBakey Department of Surgery, Division of Congenital Heart Surgery, Baylor College of Medicine, 6621 Fannin St, MC19345H, Houston, TX 77030, United States of America. Tel: +832 824 4865; Fax: +1 832/825-1905; E-mail: [email protected]
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Abstract

Anomalous origin of the left coronary artery from the right pulmonary artery in single ventricles is a very rare congenital anomaly. Failure to recognise it preoperatively may lead to adverse outcomes, including death. We report the case of a neonate with a univentricular heart in the form of a double-outlet right ventricle, mitral atresia with discrete coarctation of the aorta, and an incidental intraoperative finding of an anomalous origin of the left coronary artery from the right pulmonary artery. The patient underwent a successful repair with an uneventful postoperative course.

Keywords

Double-outlet right ventriclemitral atresiaaortic coarctationanomalous origin of the left coronary artery from the right pulmonary artery
Type
Brief Report
Information
Cardiology in the Young , Volume 27 , Issue 9 , November 2017 , pp. 1853 - 1856
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Copyright
© Cambridge University Press 2017 

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References

1. Turiy, Y, Douglas, W, Balaguru, D. Anomalous origin of coronary artery from main pulmonary artery in hypoplastic left heart syndrome. Ann Thorac Surg 2015; 100: 2346–2348.CrossRefGoogle ScholarPubMed
2. Sarris, GE, Drummond-Webb, JJ, Ebeid, MR, Latson, LA, Mee, RB. Anomalous origin of left coronary from right pulmonary artery in hypoplastic left heart syndrome. Ann Thorac Surg 1997; 64: 836–838.Google Scholar
3. Nathan, M, Emani, S, Marx, G, Pigula, F. Anomalous left coronary artery arising from the pulmonary artery in hypoplastic left hearts: case series and review of literature. J Thorac Cardiovasc Surg 2011; 142: 225–227.Google Scholar
4. Nosal, M, Omeje, IC, Poruban, R. Hypoplastic left heart syndrome with anomalous origin of left coronary artery from the right pulmonary artery: successful surgical treatment in a neonate. Eur J Cardiothorac Surg 2005; 28: 497–498.Google Scholar
5. Jaworski, R, Kansy, A, Laniewski-Wollk, P. Anomalous origin of circumflex coronary artery from right pulmonary artery in a hypoplastic left heart syndrome child. Kardiochir Torakochirurgia Pol 2014; 11: 210–212.Google Scholar
6. Malec, E, Mroczek, T, Pajak, J, Zajac, A, Kołcz, J, Januszewska, K. Hypoplastic left heart syndrome with an anomalous origin of the left coronary artery. Ann Thorac Surg 2001; 72: 2129–2130.Google Scholar
7. Saroli, T, Gelehrter, S, Gomez-Fifer, CA, van der Velde, ME, Bove, EL, Ensing, GJ. Anomalies of left coronary artery origin affecting surgical repair of hypoplastic left heart syndrome and Shone complex. Echocardiography 2008; 25: 727–731.Google Scholar
8. Bitar, FF, Kveselis, DA, Smith, FC, Byrum, CJ, Quaegebeur, JM. Double-outlet right ventricle (tetralogy of Fallot type) associated with anomalous origin of the left coronary artery from the right pulmonary artery: report of successful total repair in a 2-month-old infant. Pediatr Cardiol 1998; 19: 361–362.Google Scholar