Hostname: page-component-586b7cd67f-rcrh6 Total loading time: 0 Render date: 2024-11-24T06:49:03.805Z Has data issue: false hasContentIssue false
  • English
  • Français

Bronchogenic cysts as a cause of infantile stridor: case report and literature review

Published online by Cambridge University Press:  18 July 2011

J Goswamy ,
S de Kruijf ,
G Humphrey ,
M P Rothera  and
I A Bruce
J Goswamy*
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK
S de Kruijf
Affiliation:
Erasmus Medical School, Rotterdam, The Netherlands
G Humphrey
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK
M P Rothera
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK
I A Bruce
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK University of Manchester, UK
*
Address for correspondence: Mr J Goswamy, Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Oxford Road, Manchester M13 9WL, UK E-mail: [email protected]
Get access Rights & Permissions [Opens in a new window]

Abstract

Introduction:

Cystic lesions related to the upper airway are an unusual cause of infantile stridor. Such a lesion may exert a mass effect, with subsequent airway compromise.

Case report:

A six-month-old boy was transferred to our unit with a right-sided, level IV neck lump and a three-month history of chronic cough and, latterly, inspiratory stridor. Computed tomography revealed a large, unilocular, cystic, cervicothoracic lesion causing marked compression of the trachea. Airway endoscopy subsequently revealed the larynx to be displaced to the left, with severe external compression of the trachea from just below the subglottic level to immediately above the carina. The mediastinal lesion was excised via an external approach. The histological diagnosis was a bronchogenic cyst.

Conclusion:

Bronchogenic cysts are a rare cause of infantile stridor, and should be considered in the differential diagnosis of cystic cervical and mediastinal masses. Surgical excision is the treatment of choice.

Keywords

Bronchogenic CystInfantStridor
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 125 , Issue 10 , October 2011 , pp. 1094 - 1097
Copyright
Copyright © JLO (1984) Limited 2011

Access options

Get access to the full version of this content by using one of the access options below. (Log in options will check for institutional or personal access. Content may require purchase if you do not have access.)

Footnotes

Presented at the 139th Semon Club Meeting, 21 May 2010, Guy's Hospital, London, UK

References

1Horak, E, Bodner, J, Gassner, I, Schmid, T, Simma, B, Grassl, G et al. Congenital cystic lung disease: diagnostic and therapeutic considerations. Clin Pediatr (Phila) 2003;42:251–61CrossRefGoogle ScholarPubMed
2Estrera, AS, Landay, MJ, Pass, LJ. Mediastinal carinal bronchogenic cyst: is it's mere presence an indication for surgical excision? South Med J 1987;80:1523–6CrossRefGoogle Scholar
3Williams, HJ, Johnson, KJ. Imaging of congenital cystic lung lesions. Paediatr Respir Rev 2002;3:120–7CrossRefGoogle ScholarPubMed
4Yerman, HM, Holinger, LD. Bronchogenic cyst with tracheal involvement. Ann Otol Rhinol Laryngol 1990;99:89–93CrossRefGoogle ScholarPubMed
5Lazar, RH, Younis, RT, Bassila, MN. Bronchogenic cysts: a cause of stridor in the neonate. Am J Otolaryngol 1991;12:117–21CrossRefGoogle ScholarPubMed
6Stewart, B, Cochran, A, Iglesia, K, Speights, VO, Ruff, T. Unusual case of stridor and wheeze in an infant: tracheal bronchogenic cyst. Pediatr Pulmonol 2002;34:320–3CrossRefGoogle Scholar
7Ombrellaro, M, Feola, M, Goldthorn, JF, Shires, GT. Bronchogenic cysts: an overview. Contemp Surg 1993;42:167–71Google Scholar
8Shanmugam, G, MacArthur, K, Pollock, JC. Congenital lung malformations – antenatal and postnatal evaluation and management. Eur J Cardiothorac Surg 2005;27:45–52CrossRefGoogle ScholarPubMed
9Maier, HC. Bronchogenic cysts of the mediastinum. Ann Surg 1948;127:476–502CrossRefGoogle Scholar
10Klin, B, Springer, C, Segal, M, Eshel, G, Tabachnik, E, Vinograd, I. Recurrent cyanotic spells caused by a segmental intramural cyst of the upper trachea. Pediatr Pulmonol 1994;18:119–21CrossRefGoogle ScholarPubMed
11Nussenbaum, B, McClay, JE, Timmons, CF. Laryngeal duplication cyst. Arch Otolaryngol Head Neck Surg 2002;128:1317–20CrossRefGoogle ScholarPubMed
12Zedan, M, Elgamal, MA, Zalata, K, Nasef, N, Fouda, A. Progressive stridor: could it be congenital cystic lung disease? Acta Paediatr 2009;98:1533–6CrossRefGoogle ScholarPubMed
13Artz, GJ, Reilly, JS, Mattei, P. Stridor in an infant. Clin Pediatr 2006;45:578–81CrossRefGoogle ScholarPubMed
14Lai, P, Nguyen, LHP, Kim, PCW, Campisi, P. An unusual case of biphasic stridor in an infant: suprasternal bronchogenic cyst. J Pediatr 2006;149:424CrossRefGoogle Scholar