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Desmoplastic fibroma of the vidian canal in a child: case report

Published online by Cambridge University Press:  30 March 2011

S Peridis*
Affiliation:
Department of Otolaryngology Head and Neck Surgery, Guy's and St Thomas' NHS Foundation Trust, London, UK
M T Moonim
Affiliation:
Department of Histopathology, Guy's and St Thomas' NHS Foundation Trust, London, UK
D Roberts
Affiliation:
Department of Otolaryngology Head and Neck Surgery, Guy's and St Thomas' NHS Foundation Trust, London, UK
S Al-Sarraj
Affiliation:
Department of Clinical Neuropathology, King's College Hospital, London, UK
C Hopkins
Affiliation:
Department of Otolaryngology Head and Neck Surgery, Guy's and St Thomas' NHS Foundation Trust, London, UK
*
Address for correspondence: Mr Stamatios Peridis, Department of Otolaryngology Head and Neck Surgery, Guy's and St Thomas' NHS Foundation Trust, Guy's Hospital, Great Maze Pond, London SE1 9RT, UK E-mail: [email protected]

Abstract

Introduction:

To present a case of a child with a desmoplastic fibroma of the vidian canal, compressing the vidian nerve.

Case report:

A 12-year-old girl with several years' history of right-sided facial pain was referred to our institution. Magnetic resonance imaging and computed tomography scans showed an expansile mass involving the right vidian canal. The patient underwent a complete endoscopic surgical resection aided by the FusionTM ENT navigation system. This was performed through a transnasal, trans-septal, trans-sphenoidal route via the right nostril, and achieved macroscopic clearance with minimal peri-operative morbidity. A biopsy of the lesion showed a fibro-osseous lesion consistent with desmoplastic fibroma.

Conclusion:

Diagnosis and resection of this rare lesion at an earlier stage would have avoided delays in resolving the child's disabling pain. This emphasises the importance of early referral of unusual cases to tertiary centres.

Type
Clinical Records
Copyright
Copyright © JLO (1984) Limited 2011

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References

1Osawa, S, Rhoton, AL Jr, Seker, A, Shimizu, S, Fujii, K, Kassam, AB. Microsurgical and endoscopic anatomy of the vidian canal. Neurosurgery 2009;64:385412Google ScholarPubMed
2Moorjani, V, Stockton, V. Desmoplastic fibroma with perineural extension. AJR Am J Roentgenol 2005;185:1498–9CrossRefGoogle ScholarPubMed
3Wippold, FJ 2nd , White, FV, Jamroz, G, Haughey, B, Forsen, J. Desmoplastic fibroma of the mandible in an infant. Pediatr Radiol 2005;35:906–9CrossRefGoogle ScholarPubMed
4Ginsberg, LE, De Monte, F, Gillenwater, AM. Greater superficial petrosal nerve: anatomy and MR findings in perineural tumor spread. AJNR Am J Neuroradiol 1996;17:389–93Google Scholar
5Konno, A. Historical, pathophysiological, and therapeutic aspects of the vidian neurectomy. Curr Allergy Asthma Rep 2010;10:105–12CrossRefGoogle ScholarPubMed
6Golding-Wood, PH. Observations on petrosal and vidian neurectomy in chronic vasomotor rhinitis. J Laryngol Otol 1961;75:232–47CrossRefGoogle ScholarPubMed
7Cheong, JH, Kim, JM, Bak, KH, Kim, CH, Oh, YH, Park, DW. Bilateral vidian nerve schwannomas associated with facial nerve palsy. Case report and review of the literature. J Neurosurg 2006;104:835–9CrossRefGoogle ScholarPubMed
8Kendi, TK, Erakar, A, Saglik, Y, Yildiz, HY, Erekul, S. Desmoplastic fibroma of bone: a case report. Clin Imaging 2003;27:200–2CrossRefGoogle Scholar