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Congenital salivary fistula of an accessory parotid gland in Goldenhar syndrome

Published online by Cambridge University Press:  28 October 2011

Z Sun ,
L Sun ,
Z Zhang  and
X Ma
Z Sun
Affiliation:
Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, Beijing, China
L Sun
Affiliation:
Central Laboratory of Oral Pathology, School and Hospital of Stomatology, Peking University, Beijing, China
Z Zhang
Affiliation:
Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, Beijing, China
X Ma*
Affiliation:
Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, Beijing, China
*
Address for correspondence: Dr Xuchen Ma, Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, 22 Zhongguancun South Street, Haidian District, Beijing 100081, P R China Fax: +86 10 62173402 E-mail: [email protected]
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Abstract

Objectives:

We report two cases of congenital salivary fistula of an accessory parotid gland, and we discuss its occurrence in Goldenhar syndrome.

Methods:

Two teenagers complained of a congenital cheek fistula with constant salivary discharge. Computed tomography fistulography and sialography were performed. The diagnosis of Goldenhar syndrome was established based on clinical and imaging findings. Previously reported cases are reviewed and the clinical and radiological features summarised.

Results:

In these two patients, a salivary fistula of an accessory parotid gland was demonstrated on computed tomography fistulography, and did not communicate with Stensen's duct. Deformity of Stensen's duct and hypoplasia of the ipsilateral mandibular ramus were present. Tragal appendices have frequently been reported in such cases.

Conclusion:

A congenital cheek salivary fistula of an accessory parotid gland should be considered indicative of Goldenhar syndrome.

Keywords

ChildGoldenhar SyndromeParotid Gland, AbnormalityFistulaComputed Tomography
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 126 , Issue 1 , January 2012 , pp. 103 - 107
Copyright
Copyright © JLO (1984) Limited 2011

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