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Coronary fibromuscular dysplasia with three-vessel involvement: a rare cause of ischaemic dilated cardiomyopathy in a very young male

Part of: Advanced Imaging

Published online by Cambridge University Press:  24 March 2022

Paul-Adrian Călburean Open the ORCID record for Paul-Adrian Călburean [Opens in a new window] ,
László Hadadi Open the ORCID record for László Hadadi [Opens in a new window] ,
Roxana Rudzik  and
Dan Dobreanu
Paul-Adrian Călburean
Affiliation:
Emergency Institute for Cardiovascular Diseases and Transplantation, Tîrgu Mureş, Romania University of Medicine, Pharmacy, Science and Technology “George Emil Palade” of Tîrgu Mureş, Tîrgu Mureş, Romania
László Hadadi*
Affiliation:
Emergency Institute for Cardiovascular Diseases and Transplantation, Tîrgu Mureş, Romania
Roxana Rudzik
Affiliation:
Emergency Institute for Cardiovascular Diseases and Transplantation, Tîrgu Mureş, Romania
Dan Dobreanu
Affiliation:
Emergency Institute for Cardiovascular Diseases and Transplantation, Tîrgu Mureş, Romania University of Medicine, Pharmacy, Science and Technology “George Emil Palade” of Tîrgu Mureş, Tîrgu Mureş, Romania
*
Author for correspondence: Dr L. Hadadi, Department of Interventional Cardiology, Emergency Institute for Cardiovascular Diseases and Transplantation, str. Gheorghe Marinescu nr. 50, Tîrgu Mureş, 540136, Romania. Tel: +40265212111/280. E-mail: [email protected]
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Abstract

Coronary artery disease of non-atherosclerotic aetiology, while rare in incidence, can have a wide aetiology, such as fibromuscular dysplasia, which is a non-inflammatory arteriopathy of numerous histopathological types of fibromuscular tissue accumulation. This brief report describes the case of a 22-year-old male with a recently developed dilated cardiomyopathy and a history of aborted cardiac arrest at the age of 14 years. Coronary angiogram revealed severe three vessels disease, while optical coherence tomography established fibromuscular dysplasia as aetiology. Balloon and stent angioplasty was performed guided by fractional flow reserve with acceptable angiographic result.

Keywords

Fibromuscular dysplasiacoronary artery diseasedilated cardiomyopathy
Type
Brief Report
Information
Cardiology in the Young , Volume 32 , Issue 12 , December 2022 , pp. 2009 - 2012
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Copyright
© The Author(s), 2022. Published by Cambridge University Press

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References

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