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Case presentation: successful occlusion of congenital left ventricle to coronary sinus fistula

Published online by Cambridge University Press:  25 November 2024

Hojjat Mortezaeian ,
Avisa Tabib ,
Hamidreza Pouraliakbar  and
Amir Banazade Dardashty Open the ORCID record for Amir Banazade Dardashty [Opens in a new window]
Hojjat Mortezaeian
Affiliation:
Rajaie Cardiovascular Medical and Research Center, Iran University of Medical Sciences, Tehran, Iran
Avisa Tabib
Affiliation:
Rajaie Cardiovascular Medical and Research Center, Iran University of Medical Sciences, Tehran, Iran
Hamidreza Pouraliakbar
Affiliation:
Rajaie Cardiovascular Medical and Research Center, Iran University of Medical Sciences, Tehran, Iran
Amir Banazade Dardashty*
Affiliation:
Rajaie Cardiovascular Medical and Research Center, Iran University of Medical Sciences, Tehran, Iran
*
Corresponding author: Amir Banazade Dardashty; Email: [email protected]
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Abstract

Congenital left ventricle to coronary sinus fistulas are exceptionally rare, and only a few case reports of this condition exist. These fistulas may isolated or occur in conjunction with other CHDs. In this case report, we describe an 18-month-old boy who presented to our centre with a diagnosis of mitral valve insufficiency and a coronary sinus-type atrial septal defect. Upon echocardiographic evaluation, he was found to have a rare congenital left ventricle to coronary sinus fistula. Echocardiographic examination established the diagnosis. Contrary to initial suspicions, mitral regurgitation and atrial septal defect were not present. Instead, the echocardiogram revealed a left ventricular to coronary sinus fistula accompanied by dilation of the coronary sinus. These findings were corroborated by CT angiography. The fistula was then successfully occluded using a transcatheter method. Follow-up assessments at one-year post-procedure showed no complications and no evidence of significant shunting on echocardiography.

Keywords

coronary sinuscongenitalleft ventricle fistula
Type
Original Article
Information
Cardiology in the Young , Volume 35 , Issue 1 , January 2025 , pp. 152 - 156
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Copyright
© The Author(s), 2024. Published by Cambridge University Press

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